Copyright
©The Author(s) 2020. Published by Baishideng Publishing Group Inc. All rights reserved.
World J Clin Cases. Apr 26, 2020; 8(8): 1538-1546
Published online Apr 26, 2020. doi: 10.12998/wjcc.v8.i8.1538
Published online Apr 26, 2020. doi: 10.12998/wjcc.v8.i8.1538
Unusual presentation of congenital radioulnar synostosis with osteoporosis, fragility fracture and nonunion: A case report and review of literature
Zhan-Yu Yang, Jiang-Dong Ni, Ze Long, Le-Tian Kuang, Shi-Bin Tao, Department of Orthopedics, The Second Xiangya Hospital, Central South University, Changsha 410000, Hunan Province, China
Author contributions: Ni JD contributed to manuscript drafting; Yang ZY reviewed the literature and contributed to manuscript drafting; Long Z and Kuang LT were responsible for the follow-up and data collection; Tao SB was responsible for the revision of the manuscript; all authors approved the final version to be submitted.
Informed consent statement: Informed written consent was obtained from the guardians of the patient for publication of this report and any accompanying images.
Conflict-of-interest statement: The authors declare that they have no conflict of interest.
CARE Checklist (2016) statement: The authors have read the CARE Checklist (2016), and the manuscript was prepared and revised according to the CARE Checklist (2016).
Open-Access: This article is an open-access article that was selected by an in-house editor and fully peer-reviewed by external reviewers. It is distributed in accordance with the Creative Commons Attribution NonCommercial (CC BY-NC 4.0) license, which permits others to distribute, remix, adapt, build upon this work non-commercially, and license their derivative works on different terms, provided the original work is properly cited and the use is non-commercial. See: http://creativecommons.org/licenses/by-nc/4.0/
Corresponding author: Jiang-Dong Ni, MD, Professor, Department of Orthopedics, The Second Xiangya Hospital, Central South University, No. 139 Renmin Street, Changsha 410000, Hunan Province, China. nijiangdong001@csu.edu.cn
Received: January 8, 2020
Peer-review started: January 8, 2020
First decision: March 18, 2020
Revised: March 26, 2020
Accepted: April 10, 2020
Article in press: April 10, 2020
Published online: April 26, 2020
Processing time: 107 Days and 2.9 Hours
Peer-review started: January 8, 2020
First decision: March 18, 2020
Revised: March 26, 2020
Accepted: April 10, 2020
Article in press: April 10, 2020
Published online: April 26, 2020
Processing time: 107 Days and 2.9 Hours
Core Tip
Core tip: Congenital radioulnar synostosis is a rare deformity of the upper extremity, which is characterized by loss of rotation and a variety of functional limitations. We present a rare case of bilateral congenital proximal radioulnar synostosis with osteoporosis, fragility fracture and nonunion. This case suggests that internal fixation plus bone grafting or stimulus of osteogenesis may result in a much better outcome than expected. In addition, this case highlights that surgery should not be the first choice except for those with severe daily activity limitations, and physiotherapy is not inferior to surgical treatment.