Published online Jul 6, 2020. doi: 10.12998/wjcc.v8.i13.2885
Peer-review started: February 2, 2020
First decision: May 21, 2020
Revised: May 23, 2020
Accepted: June 4, 2020
Article in press: June 4, 2020
Published online: July 6, 2020
Processing time: 155 Days and 12.4 Hours
Multiple intraoral dermoid cysts of large magnitude generally appear in the second or third decade of life. They are rare in infants and are usually solitary. In this case, a large mass was identified in utero during prenatal exams.
We introduce a rare case on multiple dermoid cysts in the floor of the mouth of an infant who underwent two surgeries for this. Preoperative magnetic resonance imaging confirmed a large well-circumscribed cystic lesion that originated at the former midline region in the floor of the mouth in which a suspicious lesion of minute size was likely compressed by the bulkier mass and overlooked. Therefore, the infant underwent two surgeries by an intraoral approach within 9 mo. At 5 mo after the second operation, a routine follow-up ultrasound showed evidence of an additional cyst. No further surgery was planned because the tumor had no immediate effect.
This report demonstrates the importance of carefully analyzing preoperative imaging to avoid multiple operations for a seemingly isolated oral cyst.
Core tip: Herein, we describe an infant subjected to surgery on two occasions for multiple dermoid cysts within the floor of the mouth and perform a systematic review of the literature. The multiple lesions were squeezed so much that they are ignored, which lead to two sequential surgeries.