Published online Nov 26, 2019. doi: 10.12998/wjcc.v7.i22.3807
Peer-review started: July 27, 2019
First decision: September 9, 2019
Revised: September 19, 2019
Accepted: September 25, 2019
Article in press: September 25, 2019
Published online: November 26, 2019
Congenital scrotal agenesis (CSA) is very rare. There are 11 cases of congenital scrotal agenesis or absence reported in the literature, most of which are bilateral and accompanied by cryptorchidism. Only two cases of which are unilateral scrotal agenesis and not accompanied by cryptorchidism. This is the first reported case of unilateral scrotal agenesis with cryptorchidism and scrotoplasty.
A 2-year-old boy was admitted to our hospital with left cryptorchidism and ipsilateral CSA. An innovative method was used in the patient where a scrotal skin pedicle from the right part of scrotal skin was transplanted to the left side. At the same time, descent orchiopexy was performed. At the 4-mo follow-up, the left testicle was located in the scrotum and the size and shape were normal.
For unilateral CSA with ipsilateral cryptorchidism, contralateral scrotal pedicle transplantation and descent orchiopexy appear to be a successful surgical option.
Core tip: Congenital scrotal agenesis is very uncommon. More specially, this is the first reported case of unilateral scrotal agenesis with cryptorchidism. We innovatively transplanted the contralateral scrotal skin flap to the affected side and achieved satisfactory results.