Case Report
Copyright ©The Author(s) 2022. Published by Baishideng Publishing Group Inc. All rights reserved.
World J Clin Cases. Sep 16, 2022; 10(26): 9361-9367
Published online Sep 16, 2022. doi: 10.12998/wjcc.v10.i26.9361
Intrahepatic multicystic biliary hamartoma: A case report
Chen-Yu Wang, Fu-Yang Shi, Wei-Feng Huang, Yan Tang, Ting Li, Guo-Lin He
Chen-Yu Wang, Fu-Yang Shi, Wei-Feng Huang, Yan Tang, The Second Clinical Institute Clinical Medicine, Southern Medical University, Guangzhou 510515, Guangdong Province, China
Ting Li, Guo-Lin He, Department of Hepatobiliary Surgery II, Southern Medical University, Guangzhou 510282, Guangdong Province, China
Author contributions: He GL and Li T provides cases and constructs a framework for the report; Wang CY sorts out the context of the case, summarizes the characteristics of the case, and conducts a literature review; Shi FY, Huang WF and Tang Y organized the images in the article and participated in the literature review.
Informed consent statement: Informed written consent was obtained from the patients for publication of this report and any accompanying images.
Conflict-of-interest statement: All the authors report no relevant conflicts of interest for this article.
CARE Checklist (2016) statement: The authors have read the CARE Checklist (2016), and the manuscript was prepared and revised according to the CARE Checklist (2016).
Open-Access: This article is an open-access article that was selected by an in-house editor and fully peer-reviewed by external reviewers. It is distributed in accordance with the Creative Commons Attribution NonCommercial (CC BY-NC 4.0) license, which permits others to distribute, remix, adapt, build upon this work non-commercially, and license their derivative works on different terms, provided the original work is properly cited and the use is non-commercial. See: https://creativecommons.org/Licenses/by-nc/4.0/
Corresponding author: Guo-Lin He, MD, MMed, Chief Doctor, Second Department of Hepatobiliary Surgery, Southern Medical University, Zhujiang Hospital, Guangzhou 510000, Guangdong Province, China. dwtou@126.com
Received: April 6, 2022
Peer-review started: April 6, 2022
First decision: May 29, 2022
Revised: June 11, 2022
Accepted: August 5, 2022
Article in press: August 5, 2022
Published online: September 16, 2022
Abstract
BACKGROUND

Multicystic biliary hamartoma (MCBH) is a rare hamartomatous nodule of the liver, which has recently been described as a new category of hepatic nodular cystic lesion. Most of them are benign. The imaging findings are similar to those of many other hepatic cystic lesions, but MCBH also has some notable features, such as large cysts, smooth cyst walls, and lack of communication with the hepatic duct. Due to the non-specific radiology, preoperative diagnosis is difficult, and is usually diagnosed by postoperative pathology. Complete resection is the best treatment option, and the postoperative prognosis is good.

CASE SUMMARY

When the patients have MCBH, the symptoms may not very typical, and they require a combination of imaging and pathology for diagnosis. Under normal circumstances, the prognosis of MCBH is good. However, in patients with MCBH, more cases need to be observed for verification.

CONCLUSION

When the patients have MCBH, the symptoms may not very typical, and they require a combination of imaging and pathology for diagnosis. Under normal circumstances, the prognosis of MCBH is good. However, in patients with MCBH, more cases need to be observed for verification.

Keywords: Liver, Bile duct, Multicystic biliary hamartoma, Immunohistochemistry, Case report

Core Tip: Intrahepatic multicystic biliary hamartoma (MCBH) is a relatively rare disease with relatively few cases reported in the English literature. We review previously reported articles on MCBH on our essay, summarizing some of their characteristics and treatment. More importantly, we studied and interpreted a case that we found during our clinical work. In this essay, we describe his clinical manifestations, imaging performance, laboratory test results, pathological manifestations and surgery. We also discuss and summarize the characteristics of MCBH. We hope to better diagnose MCBH through imaging examination and pathological examination through our essay.