Original Research
Copyright ©The Author(s) 2001. Published by Baishideng Publishing Group Inc. All rights reserved.
World J Gastroenterol. Dec 15, 2001; 7(6): 805-810
Published online Dec 15, 2001. doi: 10.3748/wjg.v7.i6.805
Clinicopathological and molecular genetic analysis of 4 typical Chinese HNPCC families
Qi Cai, Meng-Hong Sun, Hong-Fen Lu, Tai-Ming Zhang, Shan-Jing Mo, Ye Xu, San-Jun Cai, Xiong-Zeng Zhu, Da-Ren Shi
Qi Cai, Meng-Hong Sun, Hong-Fen Lu, Tai-Ming Zhang, Xiong-Zeng Zhu, Da-Ren Shi, Department of Pathology, Department of Abdominal Surgery, Cancer Hospital/Cancer Institute, Fudan University, Shanghai 200032, China
Shan-Jing Mo, Ye Xu, San-Jun Cai, Department of Abdominal Surgery, Cancer Hospital/Cancer Institute, Fudan University, Shanghai 200032, China
Author contributions: All authors contributed equally to the work.
Supported by the Shanghai Medical Development Project, No. 993025
Correspondence to: Meng-Hong Sun, Department of Pathology, Cancer Hospital/Cancer Institute, Fudan University, 399 Lingling Road, Shanghai 200032, China. smh9618@public6.sta.net.cn
Telephone: +86-21-64175590 ext: 3357, Fax: +86-21-64174774
Received: July 5, 2001
Revised: August 19, 2001
Accepted: September 25, 2001
Published online: December 15, 2001
Abstract

AIM: To study the clinicopathological and mole cular genetic characteristics of typical Chinese hereditary nonpolyposis cotorectal cancer (HNPCC) families.

METHODS: Four typical Chinese HNPCC families were analyzed using microdissection, microsatellite instability analysis, immunostaining of hMSH2 and hMLH1 proteins and direct DNA sequencing of hMSH2 and hMLH1 genes.

RESULTS: All five tumor tissues of 4 probands from the 4 typical Chinese HNPCC families showed microsatellite instability at more than two loci (MSI-H or RER+ phenotype). Three out of the 4 cases lost hMSH2 protein expression and the other case showed no hMLH1 protein expression. Three pathological germline mutations (2 in hMSH2 and 1 in hMLH1), which had not been reported previously, were identified. The same mutations were also found in other affected members of two HNPCC families, respectively.

CONCLUSION: Typical Chinese HNPCC families showed relatively frequent germline mutation of mismatch repair genes. High-level microsatellite instability and loss of expression of mismatch repair genes correlated closely with germline mutation of mismatch repair genes. Microsatellite instability analysis and immunostaining of mismatch repair gene might serve as effective screening methods before direct DNA sequencing. It is necessary to establish clinical criteria and molecular diagnostic strategies more suitable for Chinese HNPCC families.

Keywords: colorectal neoplasm; hereditary nonpolypo sis/genetic; colorectal neoplasms, hereditary nonpolyposis/pathology; immunohi stochemistry; sequence analysis, DNA