Retrospective Study
Copyright ©The Author(s) 2019. Published by Baishideng Publishing Group Inc. All rights reserved.
World J Gastroenterol. Aug 14, 2019; 25(30): 4235-4245
Published online Aug 14, 2019. doi: 10.3748/wjg.v25.i30.4235
Natural history of children with mild Crohn’s disease
Yamini Sharma, Athos Bousvaros, Enju Liu, Julia Bender Stern
Yamini Sharma, Athos Bousvaros, Enju Liu, Julia Bender Stern, Department of Gastroenterology and Hepatology, Inflammatory Bowel Disease Center, Boston Children’s Hospital, Boston, MA 02115, United States
Author contributions: All authors helped to perform the research; Sharma Y contribution to manuscript writing, drafting conception, performing data analysis, interpreting data; Bousvaros A contribution to manuscript writing, drafting conception and design, performing data analysis, interpreting data; Liu E contribution to statistical analysis of data; Bender Stern J contribution to providing data set.
Institutional review board statement: This study was reviewed and approved by the IRB of Boston Children’s Hospital.
Informed consent statement: Patients were not required to give informed consent to the study because this was a retrospective medical chart review.
Conflict-of-interest statement: All authors declare no conflicts-of-interest related to this article.
Data sharing statement: No additional data are available.
Open-Access: This is an open-access article that was selected by an in-house editor and fully peer-reviewed by external reviewers. It is distributed in accordance with the Creative Commons Attribution Non Commercial (CC BY-NC 4.0) license, which permits others to distribute, remix, adapt, build upon this work non-commercially, and license their derivative works on different terms, provided the original work is properly cited and the use is non-commercial. See: http://creativecommons.org/licenses/by-nc/4.0/
Corresponding author: Athos Bousvaros MD, MPH, Professor, Department of Gastroenterology and Hepatology, Boston Children’s Hospital, 300 Longwood avenue, Boston, MA 02115 United States. Athos.bousvaros@childrens.harvard.edu
Telephone: +1-617-3556058
Received: January 22, 2019
Peer-review started: January 22, 2019
First decision: February 13, 2019
Revised: July 3, 2019
Accepted: July 5, 2019
Article in press: July 5, 2019
Published online: August 14, 2019
Processing time: 204 Days and 15.5 Hours
Abstract
BACKGROUND

There is a small and poorly studied population of patients with mild and limited Crohn’s disease (CD), who either spontaneously enter remission and can discontinue therapy, or be maintained on milder anti-inflammatory treatment.

AIM

To identify a group of children with mild CD who were not escalated to immunomodulators (azathioprine, mercaptopurine, or methotrexate) or biologics (infliximab or adalimumab) within the first two years after their Crohn’s diagnosis and outline the natural history and phenotypic features of these patients.

METHODS

In a retrospective chart review of the inflammatory bowel disease database at Boston Children’s Hospital we reviewed all the mild CD patient’s clinic visits, laboratory studies, and procedures for the duration of time they were followed at the center. Patients were included if they had clear diagnosis of Crohn’s disease, and they were not escalated to immunosuppressive therapies for at least 2 years after the date of diagnosis. These mild CD patients were compared to controls diagnosed at a similar time, that were treated with immunomodulators or biologics. Data that was abstracted included: Age at diagnosis, sex, disease location utilizing the Paris classification, medical treatment, surgical treatment, endoscopic findings, histology, and hospitalizations. We also analyzed differences in the phenotypic features between those with mild CD and those with moderate to severe disease.

RESULTS

Out of 1205 patients with CD diagnosed between 1990 and 2013, we identified 29 patients that met the inclusion criteria, and they were matched with 58 controls. There were no significant differences between the disease behaviors at presentation, with approximately 90% of patients in each group having inflammatory disease. However, patients with mild disease were more likely to have disease limited to the colon (31% vs 12%, P = 0.03). In contrast, patients with moderate to severe disease (aka control group) were more likely to have ileocolonic disease (70% vs 45% in the mild group, P = 0.02). Of the 29 patients, only 8 required medication escalation to immunomodulators during the period of follow-up. The primary indication for escalation to immune suppressive therapies was corticosteroid dependence. We also found that patients treated without immunomodulators or biologics for mild CD continue to exhibit histologic intestinal inflammation. Of the 29 patients, three developed significant complications of ileal disease, though only one required surgical intervention during the period of follow-up.

CONCLUSION

We identified a cohort of children with mild CD, who were able to avoid the institution of immune suppressive therapies for several years, and generally had good outcomes during the period of follow-up. While a subset of these patients will eventually require either immunosuppression or surgery, the majority of them have a good quality of life despite having low-grade intestinal inflammation. Importantly, this subset of patients has managed to avoid the potential toxicities of immune suppression for several years. The majority of these patients have either colonic disease with minimal small bowel involvement or limited ileal disease.

Keywords: Crohn’s disease; Colitis; Aminosalicylates; Antibiotics; Immunosuppression; Inflammatory bowel disease; Child; Pediatric

Core tip: We demonstrate that a higher percentage of patients with mild Crohn’s have colonic disease compared to matched controls with moderate to severe disease. We show that patients with mild disease can be maintained for several years on milder treatments and the majority can avoid escalation to immunosuppressive therapies.