Editorial
Copyright ©2009 The WJG Press and Baishideng. All rights reserved.
World J Gastroenterol. Nov 21, 2009; 15(43): 5397-5408
Published online Nov 21, 2009. doi: 10.3748/wjg.15.5397
Peutz-Jeghers syndrome: Diagnostic and therapeutic approach
Marcela Kopacova, Ilja Tacheci, Stanislav Rejchrt, Jan Bures
Marcela Kopacova, Ilja Tacheci, Stanislav Rejchrt, Jan Bures, 2nd Department of Medicine, Charles University in Praha, Faculty of Medicine at Hradec Králové, University Teaching Hospital, Sokolská 581, Hradec Králové 500 05, Czech Republic
Author contributions: Kopacova M, Tacheci I, Rejchrt S and Bures J contributed equally to this work.
Supported by Research Project MZO 00179906 From the Ministry of Health, Czech Republic
Correspondence to: Marcela Kopacova, Associate professor, MD, PhD, 2nd Department of Medicine, Charles University in Praha, Faculty of Medicine at Hradec Králové, University Teaching Hospital, Sokolská 581, Hradec Králové 500 05, Czech Republic. kopacmar@fnhk.cz
Telephone: +420-49-5834240 Fax: +420-49-5834785
Received: September 8, 2009
Revised: October 10, 2009
Accepted: October 17, 2009
Published online: November 21, 2009
Abstract

Peutz-Jeghers syndrome (PJS) is an inherited, autosomal dominant disorder distinguished by hamartomatous polyps in the gastrointestinal tract and pigmented mucocutaneous lesions. Prevalence of PJS is estimated from 1 in 8300 to 1 in 280 000 individuals. PJS predisposes sufferers to various malignancies (gastrointestinal, pancreatic, lung, breast, uterine, ovarian and testicular tumors). Bleeding, obstruction and intussusception are common complications in patients with PJS. Double balloon enteroscopy (DBE) allows examination and treatment of the small bowel. Polypectomy using DBE may obviate the need for repeated urgent operations and small bowel resection that leads to short bowel syndrome. Prophylaxis and polypectomy of the entire small bowel is the gold standard in PJS patients. Intraoperative enteroscopy (IOE) was the only possibility for endoscopic treatment of patients with PJS before the DBE era. Both DBE and IOE facilitate exploration and treatment of the small intestine. DBE is less invasive and more convenient for the patient. Both procedures are generally safe and useful. An overall recommendation for PJS patients includes not only gastrointestinal multiple polyp resolution, but also regular lifelong cancer screening (colonoscopy, upper endoscopy, computed tomography, magnetic resonance imaging or ultrasound of the pancreas, chest X-ray, mammography and pelvic examination with ultrasound in women, and testicular examination in men). Although the incidence of PJS is low, it is important for clinicians to recognize these disorders to prevent morbidity and mortality in these patients, and to perform presymptomatic testing in the first-degree relatives of PJS patients.

Keywords: Gastrointestinal endoscopy; Intraoperative period; Peutz-Jeghers syndrome; Hamartoma