Case Report
Copyright ©2005 Baishideng Publishing Group Inc. All rights reserved.
World J Gastroenterol. Apr 7, 2005; 11(13): 2032-2034
Published online Apr 7, 2005. doi: 10.3748/wjg.v11.i13.2032
An autopsy case of acute pancreatitis with a high serum IgG4 complicated by amyloidosis and rheumatoid arthritis
Tatsuki Ichikawa, Kazuhiko Nakao, Keisuke Hamasaki, Kazuaki Ohkubo, Kan Toriyama, Katsumi Eguchi
Tatsuki Ichikawa, Keisuke Hamasaki, Kazuaki Ohkubo, Katsumi Eguchi, The First Department of Internal Medicine, Nagasaki University School of Medicine, Nagasaki, Japan
Kazuhiko Nakao, Health Research Center, Nagasaki University, Nagasaki, Japan
Kan Toriyama, Department of Pathology, Institute of Tropical Medicine, Nagasaki University, Nagasaki, Japan
Author contributions: All authors contributed equally to the work.
Correspondence to: Tatsuki Ichikawa, The First Department of Internal Medicine, Nagasaki University School of Medicine, 1-7-1 Sakamoto, Nagasaki 852-8501, Japan. ichikawa@net.nagasaki-u.ac.jp
Telephone: +81-95-849-7260 Fax: +81-95-849-7270
Received: July 17, 2004
Revised: July 18, 2004
Accepted: November 4, 2004
Published online: April 7, 2005
Abstract

We report an autopsy case of acute pancreatitis with a high serum IgG4 concentration complicated by systemic amyloid A amyloidosis and rheumatoid arthritis (RA). The patient was a 42-year-old Japanese female with a 22-year history of rheumatoid arthritis. She was diagnosed with myasthenia gravis when she was 31-year old. At the onset of pancreatitis, the patient was anti-nuclear antibody-positive, and had high serum gamma globulin and IgG4 levels. Dexamethasone and conventional therapy induced clinical remission and significantly decreased the serum IgG4 and gamma globulin. However, despite the decreased disease parameters, the patient developed a bleeding pseudocyst and died of cardiac failure. In the autopsy examination, it was determined that pancreatitis was probably caused by ischemia due to vascular obstruction caused by amyloid deposition in the pancreas. Even though acute pancreatitis is a rare complication in RA patients, we speculate that an autoimmune pancreatitis-related mechanism and ischemia due to vascular obstruction by amyloid deposition might be attributable to a single source that leads to acute pancreatitis in our particular case.

Keywords: Acute pancreatitis; Rheumatoid arthritis; IgG4; Systemic amyloidosis; Autoimmune pancreatitis